Association of ectodermal dysplasia, ectrodactyly, and macular dystrophy: the EEM syndrome.

نویسندگان

  • S Ohdo
  • K Hirayama
  • T Terawaki
چکیده

We report five patients with ectodermal dysplasia, ectrodactyly associated with syndactyly or cleft hand or both, and, in addition, macular dystrophy which was presumed to be progressive, in an isolated population on a remote island in Japan. The heredity of this syndrome was thought to be autosomal recessive. Three cases have been reported so far with a combination of the same abnormalities. The parents in these cases were consanguineous.

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منابع مشابه

Distinct CDH3 mutations cause ectodermal dysplasia, ectrodactyly, macular dystrophy (EEM syndrome).

BACKGROUND EEM syndrome is the rare association of ectodermal dysplasia, ectrodactyly, and macular dystrophy. METHODS We here demonstrate through molecular analysis that EEM is caused by distinct homozygous CDH3 mutations in two previously published families. RESULTS In family 1, a missense mutation (c.965A-->T) causes a change of amino acid 322 from asparagine to isoleucine; this amino aci...

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P-cadherin is a p63 target gene with a crucial role in the developing human limb bud and hair follicle.

P-cadherin is a member of the classical cadherin family that forms the transmembrane core of adherens junctions. Recently, mutations in the P-cadherin gene (CDH3) have been shown to cause two inherited diseases in humans: hypotrichosis with juvenile macular dystrophy (HJMD) and ectodermal dysplasia, ectrodactyly, macular dystrophy (EEM syndrome). The common features of both diseases are sparse ...

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Splice site mutations in the P-cadherin gene underlie hypotrichosis with juvenile macular dystrophy.

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عنوان ژورنال:
  • Journal of medical genetics

دوره 20 1  شماره 

صفحات  -

تاریخ انتشار 1983